Advancing ambroxol for neuronopathic Gaucher disease

LILA Holding AG is a Swiss rare-disease company developing ambroxol hydrochloride as a pharmacological-chaperone therapy for the neurological manifestations of Gaucher disease types 2 and 3.

Our approach
30
nGD patients in the key studies below
0
Approved neurological treatments for nGD
<500
Estimated US patients (GD2 + GD3)
50+
Countries with decades of ambroxol use

The challenge

A fatal disease with no neurological treatment

Neuronopathic Gaucher disease (types 2 and 3) is caused by mutations in the GBA1 gene, leading to deficient glucocerebrosidase (GCase) activity. This causes toxic accumulation of glucosylceramide in the brain and progressive neurodegeneration.

Type 2 (acute neuronopathic) is the most severe form, with onset in infancy and a median survival of roughly 11–19 months. Type 3 (chronic neuronopathic) causes progressive cognitive decline, seizures, ataxia and loss of motor function through childhood and adulthood.

Current enzyme-replacement and substrate-reduction therapies manage systemic disease but do not cross the blood–brain barrier, leaving the neurological component untreated. No therapy is approved anywhere in the world for the neurological manifestations of Gaucher disease.

<500
US patients (GD2 + GD3)
11–19 mo
Median survival, GD2 (untreated)
0
Approved CNS therapies
50+
Years of clinical ambroxol use

Our science

Ambroxol as a pharmacological chaperone

Ambroxol stabilises misfolded GCase through a well-characterised molecular mechanism, and is one of few compounds shown to reach the brain at measurable concentrations.

01

Enzyme rescue in the ER

Ambroxol binds mutant GCase at the neutral pH of the endoplasmic reticulum, stabilising the misfolded protein and enabling correct folding and trafficking to the lysosome.

02

pH-dependent release

At the acidic pH of the lysosome, ambroxol dissociates from GCase, leaving the enzyme catalytically active. The net result is more functional GCase where it is needed.

03

Blood–brain barrier penetration

In the first clinical pilot study, ambroxol was detected in the cerebrospinal fluid of all treated patients (Narita et al., 2016), supporting CNS exposure.

Differentiation

Why ambroxol

Long clinical track record

Marketed as an over-the-counter mucolytic in 50+ countries since the late 1970s. Published high-dose studies in Gaucher disease have reported no serious treatment-related adverse events; long-term high-dose safety continues to be studied.

Global accessibility

Off-patent and manufactured worldwide, making it affordable even at high therapeutic doses — relevant for the low- and middle-income countries where many nGD patients live.

Class precedent

Migalastat (Galafold), approved by the FDA in 2018 for Fabry disease, validates the pharmacological-chaperone mechanism for a lysosomal storage disorder.

Evidence

Key published studies

Ambroxol has been studied in neuronopathic Gaucher disease across independent clinical centres worldwide. The studies below are the most directly relevant to the neurological forms.

First human proof-of-concept
Narita et al., 2016 · Annals of Clinical and Translational Neurology

First pilot study in neuronopathic Gaucher disease

Five patients (four GD3, one GD2) received high-dose ambroxol. Ambroxol was detected in the cerebrospinal fluid of all patients, confirming blood–brain barrier penetration, and patients showed reductions in myoclonus and seizure frequency.

N = 5Population: GD2 + GD3Key finding: CSF penetration confirmed
Largest single GD3 cohort
Lipiński et al., 2026 · Life (MDPI)

13 GD3 patients treated for 12 months

Thirteen Polish patients with type 3 Gaucher disease (L444P/L444P homozygous) on stable ERT received ambroxol at 10 mg/kg/day for one year. Neurological improvement was observed on standardised assessment, alongside reductions in selected biomarkers.

N = 13Population: GD3 (L444P homozygous)Duration: 12 months
Long-term use in GD2 infants
Aries et al., 2025 · Frontiers in Neurology

Long-term ambroxol in two GD type 2 patients

Two children with GD2 were treated with high-dose ambroxol from 1 and 4 months of age, in addition to enzyme-replacement therapy. One showed nearly age-appropriate neurocognitive and motor development after three years — in a disease form with a median survival of roughly 11–19 months.

N = 2Population: GD2 (infant onset)Centre: UMC Hamburg-Eppendorf
Longest published follow-up
Hwang et al., 2024 · American Journal of Hematology

10-year follow-up of high-dose ambroxol with ERT

The longest published follow-up of high-dose ambroxol combined with enzyme-replacement therapy in neuropathic Gaucher disease, reporting sustained neurological stability over a full decade of continuous treatment.

Duration: 10 yearsPopulation: neuropathic GDKey finding: sustained stability
Real-world high-dose use
Kim et al., 2020 · Journal of Medical Genetics

High-dose ambroxol in GD with myoclonic epilepsy

Four Korean patients with Gaucher disease and myoclonic epilepsy received high-dose ambroxol with ERT. Improvements in epilepsy and cerebellar tremor were documented in some patients at sustained high doses, with a favourable safety profile.

N = 4Population: nGD + myoclonic epilepsyKey finding: symptom improvement in a subset
All patient numbers and findings above reflect the cited peer-reviewed publications. Ambroxol is not approved by the FDA or other major regulators for the treatment of Gaucher disease; the studies referenced describe investigational and off-label use.

Contact

Get in touch

We welcome inquiries from researchers, clinicians and patient-advocacy organisations working in Gaucher disease and lysosomal storage disorders.

Email

info@lila-holdingag.com

For general inquiries and partnerships.

Location

Zurich, Switzerland

A Swiss corporation registered in the Canton of Zurich.